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GeneE
25 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
β“˜GeneE is for informational purposes only. It is not a substitute for professional medical advice, diagnosis, or treatment.
GJB6
gap junction protein beta 6
Chromosome 13 Β· 13q12.11
NCBI Gene: 10804Ensembl: ENSG00000121742.20HGNC: HGNC:4288UniProt: O95452
166PubMed Papers
23Diseases
0Drugs
11Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
gap junctioncell junctiongap junction assemblytransmembrane transportClouston syndromehearing loss, autosomal recessiveautosomal recessive nonsyndromic hearing loss 1Bautosomal dominant nonsyndromic hearing loss 3B
✦AI Summary

GJB6 encodes connexin 30, a gap junction protein essential for intercellular communication through low-molecular-weight material transport between adjacent cells 1. In the cochlea, GJB6 is predominantly expressed in supporting cells, spiral ligament, stria vascularis, and intermediate cells, where it mediates transcellular signaling, metabolic supply, and fluid homeostasis 2. The gene exhibits tissue-specific alternative splicing, with a basal promoter responsive to EGF receptor activation 1. Pathogenic GJB6 variants cause autosomal recessive (DFNB1B) and dominant (DFNA3B) non-syndromic hearing impairment, as well as Clouston-type ectodermal dysplasia. Large deletions like del(GJB6-D13S1830) act as complete loss-of-function variants, nearly abolishing GJB2 expression and causing profound hearing loss exceeding 90 dB SPL with specific cochlear structural abnormalities 3. Mutant GJB6 variants (A88V, G11R) induce keratinocyte apoptosis through caspase-3, -8, and -9 activation, elucidating syndromic dysplasia mechanisms 4. While GJB2 mutations are prevalent in hearing loss populations (up to 40% of autosomal recessive cases), GJB6 point mutations are rarely identified in some geographic populations 56, suggesting ethnic-specific mutation patterns. GJB6 remains a critical therapeutic target for gene therapy interventions in hearing impairment.

Sources cited
1
GJB6 expression localization in cochlear epithelial and connective tissues, dominant expression in lateral wall, and tissue-specific distribution patterns
PMID: 36204137
2
del(GJB6-D13S1830) deletion causes profound hearing loss and near-abolishment of Gjb2 expression in all cochlear cell types
PMID: 38605287
3
GJB6 mutant variants A88V and G11R induce apoptosis via caspase-3, -8, -9 activation in keratinocytes
PMID: 30043857
4
GJB6 encodes connexin 30, has six exons with alternative splicing, and contains EGF-responsive promoter elements
PMID: 15792634
5
GJB6 deletion del(GJB6-D13S1830) identified in hearing-impaired patients worldwide; GJB6 point mutations rare in Indian populations
PMID: 20086291
6
GJB6 mutations including del(GJB6-D13S1830) absent in eastern Indian hearing loss patients, suggesting ethnic-specific mutation patterns
PMID: 26188157
Disease Associationsβ“˜23
Clouston syndromeOpen Targets
0.82Strong
hearing loss, autosomal recessiveOpen Targets
0.64Moderate
autosomal recessive nonsyndromic hearing loss 1BOpen Targets
0.61Moderate
autosomal dominant nonsyndromic hearing loss 3BOpen Targets
0.60Moderate
autosomal recessive nonsyndromic hearing loss 1AOpen Targets
0.54Moderate
autosomal dominant nonsyndromic hearing lossOpen Targets
0.46Moderate
neurodegenerative diseaseOpen Targets
0.45Moderate
X-linked mixed deafness with perilymphatic gusherOpen Targets
0.40Moderate
X-linked mixed hearing loss with perilymphatic gusherOpen Targets
0.40Moderate
KID syndromeOpen Targets
0.38Weak
deafnessOpen Targets
0.38Weak
Palmoplantar hyperkeratosisOpen Targets
0.37Weak
nonsyndromic deafnessOpen Targets
0.34Weak
genetic disorderOpen Targets
0.34Weak
MutismOpen Targets
0.33Weak
sign or symptomOpen Targets
0.26Weak
Abruptio PlacentaeOpen Targets
0.15Weak
Hearing impairmentOpen Targets
0.13Weak
non-small cell lung carcinomaOpen Targets
0.09Suggestive
autosomal recessive nonsyndromic hearing loss 9Open Targets
0.08Suggestive
Deafness, autosomal dominant, 3BUniProt
Deafness, autosomal recessive, 1BUniProt
Ectodermal dysplasia 2, Clouston typeUniProt
Pathogenic Variants11
NM_001110219.3(GJB6):c.31G>A (p.Gly11Arg)Pathogenic
Hidrotic ectodermal dysplasia syndrome|not provided|Autosomal recessive nonsyndromic hearing loss 1B;Autosomal dominant nonsyndromic hearing loss 3B;Hidrotic ectodermal dysplasia syndrome;Autosomal recessive nonsyndromic hearing loss 1A|GJB6-related disorder
β˜…β˜…β˜†β˜†2025β†’ Residue 11
NM_001110219.3(GJB6):c.263C>T (p.Ala88Val)Pathogenic
Hidrotic ectodermal dysplasia syndrome|Autosomal recessive nonsyndromic hearing loss 1B;Autosomal dominant nonsyndromic hearing loss 3B;Hidrotic ectodermal dysplasia syndrome;Autosomal recessive nonsyndromic hearing loss 1A|Autosomal recessive nonsyndromic hearing loss 1B;Autosomal dominant nonsyndromic hearing loss 3B;X-linked mixed hearing loss with perilymphatic gusher;Hidrotic ectodermal dysplasia syndrome;Autosomal recessive nonsyndromic hearing loss 1A
β˜…β˜…β˜†β˜†2025β†’ Residue 88
NM_001110219.3(GJB6):c.148G>C (p.Asp50His)Likely pathogenic
Inborn genetic diseases|Hidrotic ectodermal dysplasia syndrome
β˜…β˜…β˜†β˜†2018β†’ Residue 50
NM_001110219.3(GJB6):c.31G>C (p.Gly11Arg)Pathogenic
Autosomal dominant nonsyndromic hearing loss 3B;Autosomal recessive nonsyndromic hearing loss 1A;Hidrotic ectodermal dysplasia syndrome;Autosomal recessive nonsyndromic hearing loss 1B
β˜…β˜†β˜†β˜†2025β†’ Residue 11
NM_001110219.3(GJB6):c.-15-1G>CLikely pathogenic
Monogenic hearing loss
β˜…β˜†β˜†β˜†2025
NM_001110219.3(GJB6):c.176G>A (p.Gly59Glu)Likely pathogenic
not provided
β˜…β˜†β˜†β˜†2019β†’ Residue 59
NM_001110219.3(GJB6):c.487del (p.Leu163fs)Likely pathogenic
Nonsyndromic Deafness
β˜…β˜†β˜†β˜†2018β†’ Residue 163
NM_001110219.3(GJB6):c.261dup (p.Ala88fs)Pathogenic
not provided
β˜†β˜†β˜†β˜†2013β†’ Residue 88
NM_001110219.3(GJB6):c.14C>T (p.Thr5Met)Pathogenic
Autosomal dominant nonsyndromic hearing loss 3B
β˜†β˜†β˜†β˜†2010β†’ Residue 5
NC_000013.11:g.(20228574_20228587)_(20460616_20460629)delPathogenic
Deafness, digenic, GJB2/GJB6
β˜†β˜†β˜†β˜†2008
NM_001110219.3(GJB6):c.110T>A (p.Val37Glu)Pathogenic
Hidrotic ectodermal dysplasia syndrome
β˜†β˜†β˜†β˜†2002β†’ Residue 37
View on ClinVar β†—
Related Genes
GJC1Protein interaction98%MYO15AProtein interaction84%GJB3Protein interaction78%CNSTProtein interaction76%GJB1Protein interaction74%MYO7AProtein interaction72%
Tissue Expression6 tissues
Bone Marrow
100%
Brain
7%
Liver
0%
Lung
0%
Ovary
0%
Heart
0%
Gene Interaction Network
Click a node to explore
GJB6GJC1MYO15AGJB3CNSTGJB1MYO7A
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt O95452
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
1.52LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.96 [0.63–1.52]
RankingsWhere GJB6 stands among ~20K protein-coding genes
  • #2,687of 20,598
    Most Researched166 Β· top quartile
  • #2,741of 5,498
    Most Pathogenic Variants11
  • #15,303of 17,882
    Most Constrained (LOEUF)1.52
Genes detectedGJB6
Sources retrieved25 papers
Response timeβ€”
πŸ“„ Sources
25β–Ό
1
PMID: 36204137
Front Mol Neurosci Β· 2022
1.00
2
Glucocorticoids, genes and brain function.
PMID: 29180230
Prog Neuropsychopharmacol Biol Psychiatry Β· 2018
0.90
3
A murine model for the del(GJB6-D13S1830) deletion recapitulating the phenotype of human DFNB1 hearing impairment: generation and functional and histopathological study.
PMID: 38605287
BMC Genomics Β· 2024
0.80
4
Mechanistic effect of the human GJB6 gene and its mutations in HaCaT cell proliferation and apoptosis.
PMID: 30043857
Braz J Med Biol Res Β· 2018
0.70
5
Human connexin 30 (GJB6), a candidate gene for nonsyndromic hearing loss: molecular cloning, tissue-specific expression, and assignment to chromosome 13q12.
PMID: 10610709
Genomics Β· 1999
0.64