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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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PIGA
phosphatidylinositol glycan anchor biosynthesis class A
Chromosome X Β· Xp22.2
NCBI Gene: 5277Ensembl: ENSG00000165195.16HGNC: HGNC:8957UniProt: A0A2K4ZA02
69PubMed Papers
23Diseases
0Drugs
49Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
protein bindingendoplasmic reticulum membranemembraneglycosylphosphatidylinositol-N-acetylglucosaminyltransferase (GPI-GnT) complexmultiple congenital anomalies-hypotonia-seizures syndrome 2paroxysmal nocturnal hemoglobinuria 1Multiple congenital anomalies-hypotonia-seizures syndrome type 2ferro-cerebro-cutaneous syndrome
✦AI Summary

PIGA encodes phosphatidylinositol N-acetylglucosaminyltransferase subunit A, the catalytic subunit of the GPI-N-acetylglucosaminyltransferase complex that catalyzes the first step of glycosylphosphatidylinositol (GPI) anchor biosynthesis 1. This enzyme transfers N-acetylglucosamine from UDP-N-acetylglucosamine to phosphatidylinositol, initiating GPI anchor assembly on the endoplasmic reticulum membrane. GPI anchors are essential for cell surface expression of complement-regulatory proteins CD55 and CD59 2. PIGA mutations cause disease through two distinct mechanisms. Somatic PIGA mutations in hematopoietic stem cell clones lead to paroxysmal nocturnal hemoglobinuria (PNH), an acquired clonal disorder characterized by hemolytic anemia, thrombosis, and bone marrow failure 1. GPI-deficient erythrocytes lack CD55 and CD59, rendering them susceptible to uncontrolled complement-mediated intravascular hemolysis 3. Clonal expansion occurs through selective advantage when GPI-negative stem cells escape T-cell-mediated autoimmune attack targeting normal hematopoietic cells 4. Conversely, hypomorphic germline PIGA mutations cause multiple congenital anomalies-hypotonia-seizures syndrome 2 and neurodevelopmental disorders with epilepsy 25. PNH is treated with complement-targeted therapy, particularly C5 inhibitors like eculizumab 1, while bone marrow transplantation remains the only cure 2.

Sources cited
1
PIGA encodes phosphatidylinositol N-acetylglucosaminyltransferase subunit A required for GPI biosynthesis; somatic mutations cause PNH with hemolytic anemia and thrombosis
PMID: 28516949
2
PIGA mutations cause PNH through GPI anchor deficiency affecting CD55 and CD59; hypomorphic germline mutations cause multiple congenital anomalies-hypotonia-seizures syndrome 2
PMID: 25237200
3
Somatic PIGA mutations result in GPI-anchored protein deficiency causing intravascular hemolysis, thrombophilia, and bone marrow failure in PNH
PMID: 37763731
4
PIGA-mutant stem cells expand through escape from T-cell-mediated autoimmune attack on normal hematopoietic cells
PMID: 40089995
5
PIGA mutations are associated with X-linked epilepsy and developmental and epileptic encephalopathies
PMID: 38612920
Disease Associationsβ“˜23
multiple congenital anomalies-hypotonia-seizures syndrome 2Open Targets
0.81Strong
paroxysmal nocturnal hemoglobinuria 1Open Targets
0.75Strong
Multiple congenital anomalies-hypotonia-seizures syndrome type 2Open Targets
0.66Moderate
ferro-cerebro-cutaneous syndromeOpen Targets
0.60Moderate
paroxysmal nocturnal hemoglobinuriaOpen Targets
0.52Moderate
infantile spasmsOpen Targets
0.37Weak
complex neurodevelopmental disorderOpen Targets
0.37Weak
epilepsy of infancy with migrating focal seizuresOpen Targets
0.37Weak
malignant migrating partial seizures of infancyOpen Targets
0.37Weak
Multiple congenital anomalies - hypotonia - seizures syndromeOpen Targets
0.37Weak
multiple congenital anomalies-hypotonia-seizures syndromeOpen Targets
0.37Weak
genetic disorderOpen Targets
0.34Weak
Epileptic encephalopathyOpen Targets
0.27Weak
Intellectual disabilityOpen Targets
0.15Weak
Neurodevelopmental abnormalityOpen Targets
0.12Weak
IGA glomerulonephritisOpen Targets
0.09Suggestive
adenomaOpen Targets
0.05Suggestive
myelodysplastic syndromeOpen Targets
0.03Suggestive
infectionOpen Targets
0.02Suggestive
idiopathic pulmonary fibrosisOpen Targets
0.02Suggestive
Multiple congenital anomalies-hypotonia-seizures syndrome 2UniProt
Neurodevelopmental disorder with epilepsy and hemochromatosisUniProt
Paroxysmal nocturnal hemoglobinuria 1UniProt
Pathogenic Variants49
NM_002641.4(PIGA):c.242G>A (p.Arg81His)Likely pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 81
NM_002641.4(PIGA):c.109A>G (p.Met37Val)Likely pathogenic
Paroxysmal nocturnal hemoglobinuria 1|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 37
NM_002641.4(PIGA):c.355C>T (p.Arg119Trp)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2|not provided|Paroxysmal nocturnal hemoglobinuria 1
β˜…β˜…β˜†β˜†2024β†’ Residue 119
NM_002641.4(PIGA):c.356G>A (p.Arg119Gln)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2|not provided|PIGA-related disorder
β˜…β˜…β˜†β˜†2024β†’ Residue 119
NM_002641.4(PIGA):c.1234C>T (p.Arg412Ter)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2|not provided
β˜…β˜…β˜†β˜†2024β†’ Residue 412
NM_002641.4(PIGA):c.145G>A (p.Val49Met)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2|Paroxysmal nocturnal hemoglobinuria 1
β˜…β˜…β˜†β˜†2024β†’ Residue 49
NM_002641.4(PIGA):c.986T>C (p.Val329Ala)Likely pathogenic
Paroxysmal nocturnal hemoglobinuria 1|Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜…β˜†β˜†2021β†’ Residue 329
NM_002641.4(PIGA):c.751T>C (p.Cys251Arg)Likely pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜†β˜†β˜†2025β†’ Residue 251
NM_002641.4(PIGA):c.293A>G (p.Tyr98Cys)Likely pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 98
NM_002641.4(PIGA):c.54_55del (p.Arg19fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 19
NM_002641.4(PIGA):c.847A>G (p.Arg283Gly)Likely pathogenic
Epileptic encephalopathy|Thyroid cancer, nonmedullary, 1|Nonpapillary renal cell carcinoma
β˜…β˜†β˜†β˜†2024β†’ Residue 283
NM_002641.4(PIGA):c.188G>C (p.Arg63Thr)Likely pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜†β˜†β˜†2023β†’ Residue 63
NM_002641.4(PIGA):c.1028del (p.Asn343fs)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜†β˜†β˜†2023β†’ Residue 343
NM_002641.4(PIGA):c.1189-2_1189-1delLikely pathogenic
not provided
β˜…β˜†β˜†β˜†2023
NM_002641.4(PIGA):c.1281_1282del (p.Phe428fs)Likely pathogenic
Paroxysmal nocturnal hemoglobinuria 1
β˜…β˜†β˜†β˜†2023β†’ Residue 428
NM_002641.4(PIGA):c.294C>A (p.Tyr98Ter)Likely pathogenic
Paroxysmal nocturnal hemoglobinuria|not provided
β˜…β˜†β˜†β˜†2022β†’ Residue 98
NM_002641.4(PIGA):c.1354G>A (p.Asp452Asn)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜†β˜†β˜†2022β†’ Residue 452
NM_002641.4(PIGA):c.350T>C (p.Phe117Ser)Pathogenic
Multiple congenital anomalies-hypotonia-seizures syndrome 2
β˜…β˜†β˜†β˜†2022β†’ Residue 117
NM_002641.4(PIGA):c.113T>C (p.Val38Ala)Likely pathogenic
not provided
β˜…β˜†β˜†β˜†2022β†’ Residue 38
NM_002641.4(PIGA):c.-63+1G>ALikely pathogenic
not provided
β˜…β˜†β˜†β˜†2021
View on ClinVar β†—
Related Genes
PGAP4Shared pathway100%PIGZShared pathway100%CWH43Shared pathway100%PIGXShared pathway100%PIGPProtein interaction100%PIGYProtein interaction100%
Tissue Expression6 tissues
Bone Marrow
100%
Lung
19%
Brain
16%
Liver
12%
Ovary
10%
Heart
9%
Gene Interaction Network
Click a node to explore
PIGAPGAP4PIGZCWH43PIGXPIGPPIGY
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt P37287
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
0.45Moderately Constrained
pLIβ“˜
0.99Intolerant
Observed/Expected LoF0.18 [0.08–0.45]
RankingsWhere PIGA stands among ~20K protein-coding genes
  • #6,829of 20,598
    Most Researched69
  • #1,355of 5,498
    Most Pathogenic Variants49 Β· top quartile
  • #2,537of 17,882
    Most Constrained (LOEUF)0.45 Β· top quartile
Genes detectedPIGA
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
Paroxysmal nocturnal hemoglobinuria.
PMID: 25237200
Blood Β· 2014
1.00
2
Paroxysmal nocturnal haemoglobinuria.
PMID: 28516949
Nat Rev Dis Primers Β· 2017
0.90
3
When does a PNH clone have clinical significance?
PMID: 34889408
Hematology Am Soc Hematol Educ Program Β· 2021
0.80
4
Pathogenesis of paroxysmal nocturnal hemoglobinuria.
PMID: 40089995
Blood Β· 2025
0.70
5
Paroxysmal Nocturnal Hemoglobinuria: Biology and Treatment.
PMID: 37763731
Medicina (Kaunas) Β· 2023
0.60