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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
β“˜GeneE is for informational purposes only. It is not a substitute for professional medical advice, diagnosis, or treatment.
PIGB
phosphatidylinositol glycan anchor biosynthesis class B
Chromosome 15 Β· 15q21.3
NCBI Gene: 9488Ensembl: ENSG00000069943.11HGNC: HGNC:8959UniProt: Q92521
24PubMed Papers
21Diseases
0Drugs
32Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
dol-P-Man:Man(2)GlcN-acyl-PI alpha-1,2-mannosyltransferase activityendoplasmic reticulum membraneGPI anchor biosynthetic processalpha-1,2-mannosyltransferase activitygenetic developmental and epileptic encephalopathyneurodegenerative diseasegenetic disorderhyperphosphatasia-intellectual disability syndrome
✦AI Summary

PIGB encodes an alpha-1,2-mannosyltransferase essential for glycosylphosphatidylinositol (GPI) anchor biosynthesis, catalyzing the transfer of the third mannose residue from dolichol-phosphate-mannose to GPI intermediates in the endoplasmic reticulum 1. This enzyme participates in the ninth step of GPI anchor biosynthesis, enabling proper cellular localization and function of GPI-anchored proteins 1. Pathogenic variants in PIGB cause early infantile epileptic encephalopathy 80 (EIEE-80), characterized by severe developmental delay, early-onset epilepsy, peripheral neuropathy, and hypomyelination 2. The disorder also encompasses acrofrontofacionasal dysostosis type 1 (AFFND1), featuring dysmorphic features, skeletal abnormalities, and intellectual disability 1. Germline PIGB mutations can contribute to paroxysmal nocturnal hemoglobinuria (PNH) through copy-neutral loss of heterozygosity, resulting in complement-mediated hemolysis and inflammatory symptoms 34. Unlike typical PIGA-related PNH, PIGB-deficient cells accumulate GPI intermediates on the cell surface, which together with complement activation cause inflammasome activation and auto-inflammatory features 4. Clinical presentation ranges from severe neurodevelopmental disorders to hematological manifestations, expanding the phenotypic spectrum of GPI biosynthesis defects.

Sources cited
1
PIGB encodes an enzyme in GPI anchor biosynthesis and causes AFFND1 with dysmorphic features and intellectual disability
PMID: 34400385
2
PIGB variants cause EIEE-80 with developmental delay, epilepsy, peripheral neuropathy, and hypomyelination
PMID: 34161862
3
Germline PIGB mutations can cause PNH through copy-neutral loss of heterozygosity
PMID: 33216889
4
PIGB-deficient cells accumulate GPI intermediates causing inflammasome activation and auto-inflammatory features
PMID: 34497235
⚠Limited data available β€” This gene has 4 indexed publications. Summary and analysis may be incomplete.
Disease Associationsβ“˜21
genetic developmental and epileptic encephalopathyOpen Targets
0.69Moderate
neurodegenerative diseaseOpen Targets
0.41Moderate
genetic disorderOpen Targets
0.19Weak
hyperphosphatasia-intellectual disability syndromeOpen Targets
0.12Weak
alcohol drinkingOpen Targets
0.11Weak
premature birthOpen Targets
0.03Suggestive
rheumatic diseaseOpen Targets
0.03Suggestive
Abnormality of the skeletal systemOpen Targets
0.03Suggestive
trauma complicationOpen Targets
0.02Suggestive
osteoarthritis, handOpen Targets
0.02Suggestive
infectionOpen Targets
0.02Suggestive
coronary artery diseaseOpen Targets
0.02Suggestive
liver diseaseOpen Targets
0.02Suggestive
cataractOpen Targets
0.02Suggestive
osteosarcomaOpen Targets
0.01Suggestive
cancerOpen Targets
0.01Suggestive
heart failureOpen Targets
0.01Suggestive
acrofrontofacionasal dysostosisOpen Targets
0.01Suggestive
colorectal carcinomaOpen Targets
0.00Suggestive
epilepsyOpen Targets
0.00Suggestive
Developmental and epileptic encephalopathy 80UniProt
Pathogenic Variants32
NM_004855.5(PIGB):c.695G>A (p.Arg232His)Pathogenic
Developmental and epileptic encephalopathy, 80|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 232
NM_004855.5(PIGB):c.392T>G (p.Leu131Ter)Pathogenic
Developmental and epileptic encephalopathy, 80|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 131
NM_004855.5(PIGB):c.91A>T (p.Lys31Ter)Pathogenic
not provided|Developmental and epileptic encephalopathy, 80
β˜…β˜…β˜†β˜†2025β†’ Residue 31
NM_004855.5(PIGB):c.847-10A>GPathogenic
Developmental and epileptic encephalopathy, 80|not provided
β˜…β˜…β˜†β˜†2024
NM_004855.5(PIGB):c.1611A>G (p.Ile537Met)Pathogenic
Developmental and epileptic encephalopathy, 80|not provided
β˜…β˜…β˜†β˜†2023β†’ Residue 537
NM_004855.5(PIGB):c.795-1G>CLikely pathogenic
Developmental and epileptic encephalopathy, 80|not provided
β˜…β˜…β˜†β˜†2023
NM_004855.5(PIGB):c.18dup (p.Lys7fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2026β†’ Residue 7
NM_004855.5(PIGB):c.840del (p.Phe280fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 280
NM_004855.5(PIGB):c.663C>G (p.Tyr221Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 221
NM_004855.5(PIGB):c.211C>T (p.Arg71Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 71
NM_004855.5(PIGB):c.795-2A>GLikely pathogenic
not provided
β˜…β˜†β˜†β˜†2025
NM_004855.5(PIGB):c.840dup (p.Gly281fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2024β†’ Residue 281
NM_004855.5(PIGB):c.502C>T (p.Gln168Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2024β†’ Residue 168
NM_004855.5(PIGB):c.1152G>A (p.Trp384Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2024β†’ Residue 384
NM_004855.5(PIGB):c.318G>A (p.Trp106Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2024β†’ Residue 106
NM_004855.5(PIGB):c.463G>C (p.Asp155His)Likely pathogenic
Developmental and epileptic encephalopathy, 80
β˜…β˜†β˜†β˜†2024β†’ Residue 155
NM_004855.5(PIGB):c.795-19T>GLikely pathogenic
not provided
β˜…β˜†β˜†β˜†2024
NM_004855.5(PIGB):c.1337+1G>ALikely pathogenic
not provided
β˜…β˜†β˜†β˜†2023
NM_004855.5(PIGB):c.970_973del (p.Leu324fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2023β†’ Residue 324
NM_004855.5(PIGB):c.913_920del (p.Ser305fs)Pathogenic
not provided
β˜…β˜†β˜†β˜†2023β†’ Residue 305
View on ClinVar β†—
Related Genes
PGAP4Shared pathway100%PIGZShared pathway100%CWH43Shared pathway100%PIGXShared pathway100%PIGPProtein interaction100%PIGYProtein interaction100%
Tissue Expression6 tissues
Bone Marrow
100%
Lung
46%
Ovary
41%
Liver
40%
Brain
28%
Heart
25%
Gene Interaction Network
Click a node to explore
PIGBPGAP4PIGZCWH43PIGXPIGPPIGY
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt Q92521
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
1.10LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.70 [0.46–1.10]
RankingsWhere PIGB stands among ~20K protein-coding genes
  • #13,273of 20,598
    Most Researched24
  • #1,768of 5,498
    Most Pathogenic Variants32
  • #11,198of 17,882
    Most Constrained (LOEUF)1.10
Genes detectedPIGB
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
A novel intronic variant in PIGB in Acrofrontofacionasal dysostosis type 1 patients expands the spectrum of phenotypes associated with GPI biosynthesis defects.
PMID: 34400385
Bone Β· 2021
1.00
2
Paroxysmal nocturnal hemoglobinuria caused by CN-LOH of constitutional PIGB mutation and 70-kbp microdeletion on 15q.
PMID: 33216889
Blood Adv Β· 2020
0.90
3
Cost-effectiveness of procedure-less intragastric balloon therapy as substitute or complement to bariatric surgery.
PMID: 34319992
PLoS One Β· 2021
0.80
4
[Novel therapeutics for paroxysmal nocturnal hemoglobinuria].
PMID: 34108330
Rinsho Ketsueki Β· 2021
0.70
5
Whole-Exome Sequencing Indicated New Candidate Genes Associated with Unilateral Cryptorchidism in Pigs.
PMID: 36758533
Sex Dev Β· 2023
0.60