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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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SIX6
SIX homeobox 6
Chromosome 14 Β· 14q23.1
NCBI Gene: 4990Ensembl: ENSG00000184302.7HGNC: HGNC:10892UniProt: O95475
55PubMed Papers
21Diseases
0Drugs
8Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
RNA polymerase II cis-regulatory region sequence-specific DNA bindingsequence-specific double-stranded DNA bindingtranscription regulator complexeye developmentMicrophthalmia - cataractopen-angle glaucomaglaucomalow tension glaucoma
✦AI Summary

SIX6 (SIX homeobox 6) is a homeodomain transcription factor that plays critical roles in eye development and circadian rhythm regulation. The protein functions as a DNA-binding transcription factor with RNA polymerase II-specific activity, primarily expressed in developing and adult retinal tissues 1. SIX6 is essential for early eye field formation, optic vesicle development, and retinal differentiation, working alongside other homeodomain factors like Pax6, Lhx2, and Six3 to control cell fate determination during retinogenesis 2. The gene also functions in suprachiasmatic nucleus (SCN) development, where it is required for proper circadian pacemaker function and vasoactive intestinal peptide expression 3. Disease relevance is significant, with SIX6 variants strongly associated with primary open-angle glaucoma (POAG) across multiple populations 4. Novel pathogenic mutations like p.R116G and p.R116E have been identified in POAG patients, with these variants predicted to disrupt DNA-protein interactions and correlate with earlier disease onset and more severe visual field damage 5. SIX6 haploinsufficiency due to chr14 deletions causes bilateral anophthalmia and pituitary anomalies, demonstrating its crucial role in craniofacial development 1. The gene's function appears conserved across species, with variants also conferring glaucoma susceptibility in dogs 6.

Sources cited
1
SIX6 is a homeodomain transcription factor expressed in developing and adult retina, with haploinsufficiency causing bilateral anophthalmia and pituitary anomalies
PMID: 10512683
2
SIX6 functions in early eye development including eye field formation, optic vesicle development, and retinal differentiation alongside other homeodomain factors
PMID: 35817658
3
SIX6 is required for suprachiasmatic nucleus development, circadian pacemaker function, and vasoactive intestinal peptide expression
PMID: 31705443
4
SIX6 variants are strongly associated with primary open-angle glaucoma across multiple populations
PMID: 31284308
5
Novel pathogenic SIX6 mutations p.R116G and p.R116E are found in POAG patients and correlate with disease severity
PMID: 29405792
6
SIX6 function is conserved across species, with variants conferring glaucoma susceptibility in dogs
PMID: 41533905
Disease Associationsβ“˜21
Microphthalmia - cataractOpen Targets
0.73Strong
open-angle glaucomaOpen Targets
0.57Moderate
glaucomaOpen Targets
0.51Moderate
low tension glaucomaOpen Targets
0.43Moderate
Developmental cataractOpen Targets
0.43Moderate
early-onset non-syndromic cataractOpen Targets
0.43Moderate
sclerocorneaOpen Targets
0.43Moderate
neurodegenerative diseaseOpen Targets
0.41Moderate
isolated anophthalmia-microphthalmia syndromeOpen Targets
0.37Weak
refractive errorOpen Targets
0.37Weak
microphthalmiaOpen Targets
0.36Weak
MicrocorneaOpen Targets
0.34Weak
NystagmusOpen Targets
0.34Weak
congenital cornea planaOpen Targets
0.34Weak
cornea planaOpen Targets
0.34Weak
prostate cancerOpen Targets
0.31Weak
Alzheimer diseaseOpen Targets
0.27Weak
lysosomal storage diseaseOpen Targets
0.27Weak
multiple sclerosisOpen Targets
0.27Weak
Parkinson diseaseOpen Targets
0.27Weak
Optic disk anomalies with retinal and/or macular dystrophyUniProt
Pathogenic Variants8
NM_007374.3(SIX6):c.532_536del (p.Asn178fs)Likely pathogenic
Colobomatous optic disc-macular atrophy-chorioretinopathy syndrome|not provided
β˜…β˜…β˜†β˜†2021β†’ Residue 178
NM_007374.3(SIX6):c.105G>A (p.Trp35Ter)Likely pathogenic
not provided
β˜…β˜†β˜†β˜†2024β†’ Residue 35
NM_007374.3(SIX6):c.380del (p.Asp127fs)Likely pathogenic
See cases
β˜…β˜†β˜†β˜†2020β†’ Residue 127
NM_007374.3(SIX6):c.549C>G (p.Asp183Glu)Likely pathogenic
Colobomatous optic disc-macular atrophy-chorioretinopathy syndrome
β˜…β˜†β˜†β˜†2020β†’ Residue 183
NM_007374.3(SIX6):c.-227_572+235delPathogenic
Microphthalmia;Cornea plana;Sclerocornea;Developmental cataract
β˜…β˜†β˜†β˜†
NM_007374.3(SIX6):c.433G>T (p.Glu145Ter)Likely pathogenic
Colobomatous optic disc-macular atrophy-chorioretinopathy syndrome
β˜…β˜†β˜†β˜†β†’ Residue 145
NM_007374.3(SIX6):c.547G>C (p.Asp183His)Pathogenic
Nystagmus;Microcornea;Developmental cataract;Sclerocornea
β˜…β˜†β˜†β˜†β†’ Residue 183
NM_007374.3(SIX6):c.110T>C (p.Leu37Pro)Pathogenic
Colobomatous optic disc-macular atrophy-chorioretinopathy syndrome
β˜†β˜†β˜†β˜†2015β†’ Residue 37
View on ClinVar β†—
Related Genes
TLE1Protein interaction92%OTX2Protein interaction89%DACH1Protein interaction88%TLE5Protein interaction77%VSX2Protein interaction73%EYA2Protein interaction73%
Tissue Expression6 tissues
Brain
100%
Liver
0%
Ovary
0%
Heart
0%
Lung
0%
Bone Marrow
0%
Gene Interaction Network
Click a node to explore
SIX6TLE1OTX2DACH1TLE5VSX2EYA2
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt O95475
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
0.92LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.59 [0.39–0.92]
RankingsWhere SIX6 stands among ~20K protein-coding genes
  • #8,248of 20,598
    Most Researched55
  • #3,084of 5,498
    Most Pathogenic Variants8
  • #8,462of 17,882
    Most Constrained (LOEUF)0.92
Genes detectedSIX6
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
Cell fate decisions, transcription factors and signaling during early retinal development.
PMID: 35817658
Prog Retin Eye Res Β· 2022
1.00
2
Association of Polymorphisms at the SIX1-SIX6 Locus With Primary Open-Angle Glaucoma.
PMID: 31284308
Invest Ophthalmol Vis Sci Β· 2019
0.90
3
Identification and genotype phenotype correlation of novel mutations in SIX6 gene in primary open angle glaucoma.
PMID: 29405792
Ophthalmic Genet Β· 2018
0.80
4
CRISPR Generated SIX6 and POU4F2 Reporters Allow Identification of Brain and Optic Transcriptional Differences in Human PSC-Derived Organoids.
PMID: 34869356
Front Cell Dev Biol Β· 2021
0.70
5
Genomic cloning and characterization of the human homeobox gene SIX6 reveals a cluster of SIX genes in chromosome 14 and associates SIX6 hemizygosity with bilateral anophthalmia and pituitary anomalies.
PMID: 10512683
Genomics Β· 1999
0.60