HomeAboutRankingsData Sources
Β© 2026 GeneE
🧬
GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 15 days ago
β“˜GeneE is for informational purposes only. It is not a substitute for professional medical advice, diagnosis, or treatment.
BLOC1S6
biogenesis of lysosomal organelles complex 1 subunit 6
Chromosome 15 Β· 15q21.1
NCBI Gene: 26258Ensembl: ENSG00000104164.12HGNC: HGNC:8549UniProt: B3KY40
55PubMed Papers
21Diseases
0Drugs
27Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
positive regulation of pigment cell differentiationcytoplasmendosome to melanosome transportidentical protein bindingHermansky-Pudlak syndrome 9Hermansky-Pudlak syndromeHermansky-Pudlak syndrome type 9Hermansky-Pudlak syndrome type 7
✦AI Summary

BLOC1S6 encodes a component of the BLOC-1 complex essential for biogenesis of lysosome-related organelles (LROs), particularly platelet dense granules and melanosomes 1. The protein functions in concert with the AP-3 complex to target membrane proteins into vesicles for delivery to axons and nerve terminals, and associates with SNARE proteins to facilitate neurite extension and vesicle docking/fusion [UniProt Function]. BLOC1S6 also participates in melanosome transport and organization, with regulatory variants affecting melanin levels and skin pigmentation diversity in African populations 2. The gene shows upregulation during epithelial-mesenchymal transition induced by extracellular ATP, implicating it in cancer cell invasion pathways 3. Biallelic BLOC1S6 mutations cause Hermansky-Pudlak syndrome type 9 (HPS-9), an autosomal recessive disorder characterized by oculocutaneous albinism, platelet storage pool disease with absent dense granules, and bleeding diathesis 456. BLOC1S6 downregulation also mediates platelet dense granule deficiency in RUNX1 haplodeficiency 1. Disease models indicate BLOC1S6 mutations may increase susceptibility to alveolitis through enhanced inflammatory mediator expression 7.

Sources cited
1
BLOC1S6 regulatory variants impact melanin levels in vitro and modulate human skin color diversity
PMID: 38200130
2
BLOC1S6 is upregulated in epithelial-mesenchymal transition and has potential roles in EMT and cancer cell invasion
PMID: 35847855
3
BLOC1S6 mutations cause Hermansky-Pudlak syndrome type 9 with oculocutaneous albinism and platelet dense granule absence
PMID: 33543539
4
BLOC1S6/PLDN is a RUNX1 target gene; its downregulation causes platelet dense granule deficiency
PMID: 28075530
5
Homozygous BLOC1S6 deletion causes HPS-9 with oculocutaneous albinism and bleeding diathesis
PMID: 39187771
6
BLOC1S6 mutations in AT2 cells increase macrophage chemotactic protein-1, suggesting susceptibility to alveolitis
PMID: 29190429
7
BLOC1S6 compound heterozygous variants cause HPS-9 with platelet storage pool disease and absent dense granules
PMID: 32245340
Disease Associationsβ“˜21
Hermansky-Pudlak syndrome 9Open Targets
0.77Strong
Hermansky-Pudlak syndromeOpen Targets
0.58Moderate
Hermansky-Pudlak syndrome type 9Open Targets
0.58Moderate
Hermansky-Pudlak syndrome type 7Open Targets
0.37Weak
tooth diseaseOpen Targets
0.26Weak
genetic disorderOpen Targets
0.19Weak
autoinflammatory syndromeOpen Targets
0.12Weak
Griscelli diseaseOpen Targets
0.08Suggestive
Griscelli disease type 3Open Targets
0.07Suggestive
Griscelli syndrome type 3Open Targets
0.07Suggestive
Abnormality of the skeletal systemOpen Targets
0.06Suggestive
Griscelli disease type 1Open Targets
0.06Suggestive
Griscelli syndrome type 1Open Targets
0.06Suggestive
Tietz syndromeOpen Targets
0.06Suggestive
oculocutaneous albinism type 3Open Targets
0.06Suggestive
uncombable hair syndromeOpen Targets
0.06Suggestive
Microcephaly - albinism - digital anomaliesOpen Targets
0.06Suggestive
microcephaly-albinism-digital anomalies syndromeOpen Targets
0.06Suggestive
systemic inflammatory response syndromeOpen Targets
0.06Suggestive
Neurofibromatosis type 6Open Targets
0.06Suggestive
Hermansky-Pudlak syndrome 9UniProt
Pathogenic Variants27
NM_012388.4(BLOC1S6):c.335dup (p.His112fs)Pathogenic
Hermansky-Pudlak syndrome 9|Hermansky-Pudlak syndrome
β˜…β˜…β˜†β˜†2025β†’ Residue 112
NM_012388.4(BLOC1S6):c.200C>G (p.Ser67Ter)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜…β˜†β˜†2023β†’ Residue 67
NM_012388.4(BLOC1S6):c.205C>T (p.Gln69Ter)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2025β†’ Residue 69
NM_012388.4(BLOC1S6):c.224+1G>APathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2025
NM_012388.4(BLOC1S6):c.312+1G>TLikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024
NM_012388.4(BLOC1S6):c.83-1G>ALikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024
NM_012388.4(BLOC1S6):c.296T>A (p.Leu99Ter)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024β†’ Residue 99
NC_000015.10:g.45592135delPathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024
NM_012388.4(BLOC1S6):c.88del (p.Ser30fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024β†’ Residue 30
NM_012388.4(BLOC1S6):c.82+1_82+8delLikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2024
NM_012388.4(BLOC1S6):c.203_207del (p.Lys68fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023β†’ Residue 68
NM_012388.4(BLOC1S6):c.232C>T (p.Gln78Ter)Pathogenic
Hermansky-Pudlak syndrome 9|Hermansky-Pudlak syndrome
β˜…β˜†β˜†β˜†2023β†’ Residue 78
NM_012388.4(BLOC1S6):c.82+1G>ALikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023
NM_012388.4(BLOC1S6):c.157del (p.Ala53fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023β†’ Residue 53
NM_012388.4(BLOC1S6):c.313-1G>ALikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023
NM_012388.4(BLOC1S6):c.33_34del (p.Ala12fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023β†’ Residue 12
NM_012388.4(BLOC1S6):c.7_22dup (p.Ser8fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023β†’ Residue 8
NM_012388.4(BLOC1S6):c.245T>A (p.Leu82Ter)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2023β†’ Residue 82
NM_012388.4(BLOC1S6):c.82+1G>TLikely pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2022
NM_012388.4(BLOC1S6):c.89del (p.Ser30fs)Pathogenic
Hermansky-Pudlak syndrome 9
β˜…β˜†β˜†β˜†2021β†’ Residue 30
View on ClinVar β†—
Related Genes
MIPOL1Protein interaction100%RPAP2Protein interaction100%VAMP2Protein interaction100%HPS1Protein interaction99%SNAPINProtein interaction99%HPS4Protein interaction94%
Tissue Expression6 tissues
Bone Marrow
100%
Brain
53%
Heart
49%
Ovary
44%
Liver
35%
Lung
31%
Gene Interaction Network
Click a node to explore
BLOC1S6MIPOL1RPAP2VAMP2HPS1SNAPINHPS4
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt Q9UL45
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
1.50LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF1.01 [0.70–1.50]
RankingsWhere BLOC1S6 stands among ~20K protein-coding genes
  • #8,172of 20,598
    Most Researched55
  • #1,911of 5,498
    Most Pathogenic Variants27
  • #15,169of 17,882
    Most Constrained (LOEUF)1.50
Genes detectedBLOC1S6
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
PMID: 20301464
1.00
2
Integrative functional genomic analyses identify genetic variants influencing skin pigmentation in Africans.
PMID: 38200130
Nat Genet Β· 2024
0.90
3
From Transcriptomics, Metabolomics to Functional Studies: Extracellular ATP Induces TGF-Ξ²-Like Epithelial Mesenchymal Transition in Lung Cancer Cells.
PMID: 35847855
Front Oncol Β· 2022
0.80
4
The first Hermansky-Pudlak syndrome type 9 patient with two novel variants in Chinese population.
PMID: 33543539
J Dermatol Β· 2021
0.70
5
Dysregulation of PLDN (pallidin) is a mechanism for platelet dense granule deficiency in RUNX1 haplodeficiency.
PMID: 28075530
J Thromb Haemost Β· 2017
0.60