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25 sources retrieved · Most recent: April 2026 · Index updated 14 days ago
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GAA
alpha glucosidase
Chromosome 17 · 17q25.3
NCBI Gene: 2548Ensembl: ENSG00000171298.16HGNC: HGNC:4065UniProt: P10253
212PubMed Papers
22Diseases
5Drugs
743Pathogenic Variants
RESEARCH IMPACT
TrendingVariant-Rich
CLINICAL
FDA Approved TargetOMIM Disease Gene
DATA QUALITY
✓ Experimental GO Evidence✓ Swiss-Prot Reviewed
lysosomealpha-1,4-glucosidase activityglycophagylysosome organizationGlycogen storage disease due to acid maltase deficiencyglycogen storage disease IIglycogen storage disease due to acid maltase deficiency, infantile onsetglycogen storage disease due to acid maltase deficiency, late-onset
✦AI Summary

GAA (acid α-glucosidase) is a lysosomal enzyme essential for glycogen catabolism. It hydrolyzes α-1,4-linked glycosidic bonds with highest activity, and can also process α-1,6-linked glucans 1. The enzyme functions within lysosomes to degrade glycogen to glucose, supporting normal cellular metabolism 2. GAA deficiency causes Pompe disease, a neuromuscular lysosomal disorder characterized by pathological glycogen accumulation in muscle, heart, and other tissues 1. Two clinical phenotypes exist: infantile-onset Pompe disease (IOPD) with near-complete GAA deficiency presenting at birth and fatal by age 2 without treatment, and late-onset Pompe disease (LOPD) with partial GAA activity causing progressive muscle weakness and respiratory dysfunction 1. Among 1,079 Pompe disease patients, 2,075 GAA variants were identified, with clinical severity correlating to residual enzyme activity 3. Currently, enzyme replacement therapy (ERT) with recombinant human GAA represents standard care, with second-generation formulations (avalglucosidase alfa, cipaglucosidase alfa) offering improved cellular uptake and efficacy 24. Gene therapy using AAV9 vectors delivering GAA is emerging as potentially curative; early clinical trials in IOPD patients demonstrated cardiac and motor improvements 5, while LOPD trials show promise for discontinuing ERT post-therapy 1.

Sources cited
1
GAA hydrolyzes glycogen to glucose; IOPD and LOPD phenotypes and their disease progression; gene therapy approaches
PMID: 39134822
2
GAA deficiency causes intralysosomal glycogen accumulation; ERT with recombinant human GAA; second-generation therapies and their mechanisms
PMID: 40237692
3
GAA variant frequency and distribution in Pompe disease; correlation between variants and disease phenotypes in 1,079 patients
PMID: 31342611
4
AAV9-mediated gene therapy for IOPD; clinical outcomes including cardiac and motor improvements over 52 weeks
PMID: 40561529
5
Cipaglucosidase alfa approval as second-generation ERT for late-onset Pompe disease
PMID: 37184753
Disease Associationsⓘ22
Glycogen storage disease due to acid maltase deficiencyOpen Targets
0.88Strong
glycogen storage disease IIOpen Targets
0.88Strong
glycogen storage disease due to acid maltase deficiency, infantile onsetOpen Targets
0.68Moderate
glycogen storage disease due to acid maltase deficiency, late-onsetOpen Targets
0.62Moderate
disorder of glycogen metabolismOpen Targets
0.61Moderate
type 2 diabetes mellitusOpen Targets
0.58Moderate
Abnormality of the cardiovascular systemOpen Targets
0.54Moderate
diabetes mellitusOpen Targets
0.47Moderate
Glycogen storage disease due to glycogenin deficiencyOpen Targets
0.39Weak
myopathyOpen Targets
0.36Weak
genetic disorderOpen Targets
0.34Weak
glycogen storage disease due to glycogen branching enzyme deficiencyOpen Targets
0.34Weak
glycoprotein storage diseaseOpen Targets
0.34Weak
Elevated circulating creatine kinase concentrationOpen Targets
0.33Weak
glycogen storage disease due to glucose-6-phosphatase deficiency type IAOpen Targets
0.33Weak
isolated asymptomatic elevation of creatine phosphokinaseOpen Targets
0.33Weak
Abnormality of metabolism/homeostasisOpen Targets
0.27Weak
Acute rhabdomyolysisOpen Targets
0.27Weak
Rare genetic deafnessOpen Targets
0.27Weak
type 1 diabetes mellitusOpen Targets
0.26Weak
Pompe disease, infantile-onsetUniProt
Pompe disease, late-onsetUniProt
Pathogenic Variants743
NM_000152.5(GAA):c.1843G>A (p.Gly615Arg)Pathogenic
Glycogen storage disease, type II|not provided
★★★☆2026→ Residue 615
NM_000152.5(GAA):c.1552-2A>CPathogenic
not provided|Glycogen storage disease, type II
★★★☆2026
NM_000152.5(GAA):c.1841C>T (p.Thr614Met)Likely pathogenic
not provided|Glycogen storage disease, type II|Rare genetic deafness
★★★☆2026→ Residue 614
NM_000152.5(GAA):c.1831G>A (p.Gly611Ser)Likely pathogenic
Glycogen storage disease, type II|Cardiovascular phenotype|not provided
★★★☆2026→ Residue 611
NM_000152.5(GAA):c.1781G>C (p.Arg594Pro)Likely pathogenic
not provided|Glycogen storage disease, type II
★★★☆2026→ Residue 594
NM_000152.5(GAA):c.1781G>A (p.Arg594His)Pathogenic
Glycoprotein storage disease|Glycogen storage disease, type II|not provided
★★★☆2026→ Residue 594
NM_000152.5(GAA):c.1754+2T>GLikely pathogenic
not provided|Glycogen storage disease, type II|Papillary renal cell carcinoma type 1
★★★☆2026
NM_000152.5(GAA):c.1438-2A>CLikely pathogenic
not provided|Glycogen storage disease, type II
★★★☆2026
NM_000152.5(GAA):c.692+1G>APathogenic
Glycogen storage disease, type II
★★★☆2026
NM_000152.5(GAA):c.1754+2T>APathogenic
Glycogen storage disease, type II
★★★☆2026
NM_000152.5(GAA):c.1670T>G (p.Ile557Ser)Likely pathogenic
Glycogen storage disease, type II
★★★☆2026→ Residue 557
NM_000152.5(GAA):c.1241del (p.Phe414fs)Pathogenic
Glycogen storage disease, type II
★★★☆2026→ Residue 414
NM_000152.5(GAA):c.2646+2T>GLikely pathogenic
Glycogen storage disease, type II
★★★☆2025
NM_000152.5(GAA):c.1562A>T (p.Glu521Val)Pathogenic
Glycogen storage disease, type II|not provided
★★★☆2025→ Residue 521
NM_000152.5(GAA):c.1124G>T (p.Arg375Leu)Pathogenic
Glycogen storage disease, type II|not provided
★★★☆2025→ Residue 375
NM_000152.5(GAA):c.1669A>T (p.Ile557Phe)Pathogenic
Glycogen storage disease, type II|not provided
★★★☆2025→ Residue 557
NM_000152.5(GAA):c.643G>T (p.Glu215Ter)Pathogenic
Glycogen storage disease, type II
★★★☆2025→ Residue 215
NM_000152.5(GAA):c.2040+1G>TPathogenic
Glycogen storage disease, type II|not provided|Gastric cancer
★★★☆2025
NM_000152.5(GAA):c.1754+2T>CLikely pathogenic
Glycogen storage disease, type II
★★★☆2025
NM_000152.5(GAA):c.378G>A (p.Trp126Ter)Pathogenic
Glycogen storage disease, type II
★★★☆2025→ Residue 126
View on ClinVar ↗
Drug Targets5
CELGOSIVIRPhase II
Alpha glucosidase inhibitor
chronic hepatitis C virus infection
DUVOGLUSTATPhase III
Lysosomal alpha-glucosidase stabiliser
Glycogen storage disease due to acid maltase deficiency
DUVOGLUSTAT HYDROCHLORIDEPhase II
Lysosomal alpha-glucosidase stabiliser
Glycogen storage disease due to acid maltase deficiency
MIGLITOLApproved
Lysosomal alpha-glucosidase inhibitor
type 2 diabetes mellitus
VOGLIBOSEApproved
Alpha glucosidase inhibitor
type 2 diabetes mellitus
Related Genes
MGAMProtein interaction97%SIProtein interaction97%AMY1BProtein interaction94%AMY2AProtein interaction94%AMY2BProtein interaction94%GLAProtein interaction94%
Tissue Expression6 tissues
Lung
100%
Liver
93%
Heart
60%
Brain
41%
Ovary
38%
Bone Marrow
29%
Gene Interaction Network
Click a node to explore
GAAMGAMSIAMY1BAMY2AAMY2BGLA
PROTEIN STRUCTURE
Preparing viewer…
PDB8CB1 · 1.75 Å · X-ray
View on RCSB ↗
Constraintⓘ
LOEUFⓘ
1.01LoF Tolerant
pLIⓘ
0.00Tolerant
Observed/Expected LoF0.84 [0.71–1.01]
RankingsWhere GAA stands among ~20K protein-coding genes
  • #1,960of 20,598
    Most Researched212 · top 10%
  • #556of 1,025
    FDA-Approved Drug Targets2
  • #61of 5,498
    Most Pathogenic Variants743 · top 5%
  • #9,783of 17,882
    Most Constrained (LOEUF)1.01
Genes detectedGAA
Sources retrieved25 papers
Response time—
📄 Sources
25▼
1
AAV9-Mediated Gene Therapy for Infantile-Onset Pompe's Disease.
PMID: 40561529
N Engl J Med · 2025
1.00
2
GAA variants and phenotypes among 1,079 patients with Pompe disease: Data from the Pompe Registry.
PMID: 31342611
Hum Mutat · 2019
0.90
3
Advances in Pompe Disease Treatment: From Enzyme Replacement to Gene Therapy.
PMID: 39134822
Mol Diagn Ther · 2024
0.80
4
Ganoderic acid A inhibits ox-LDL-induced THP-1-derived macrophage inflammation and lipid deposition via Notch1/PPARγ/CD36 signaling.
PMID: 34329545
Adv Clin Exp Med · 2021
0.70
5
Complete nanopore repeat sequencing of SCA27B (GAA-
PMID: 38816190
J Neurol Neurosurg Psychiatry · 2024
0.68