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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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NADSYN1
NAD synthetase 1
Chromosome 11 Β· 11q13.4
NCBI Gene: 55191Ensembl: ENSG00000172890.14HGNC: HGNC:29832UniProt: Q6IA69
51PubMed Papers
21Diseases
0Drugs
13Pathogenic Variants
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
NAD+ synthase (glutamine-hydrolyzing) activityprotein binding'de novo' NAD+ biosynthetic process from L-tryptophancytoplasmvertebral, cardiac, renal, and limb defects syndrome 3congenital vertebral-cardiac-renal anomalies syndromeUlbright-Hodes syndromeneurodegenerative disease
✦AI Summary

NADSYN1 encodes NAD synthetase 1, which catalyzes the final ATP-dependent step of nicotinamide adenine dinucleotide (NAD) de novo synthesis, converting deamido-NAD to NAD using L-glutamine as a nitrogen source 1. This enzyme is essential for cellular metabolism and organ embryogenesis, operating primarily in the cytoplasm and cytosol. Biallelic loss-of-function variants in NADSYN1 cause congenital NAD deficiency disorder (CNDD), characterized by vertebral, cardiac, renal, and limb defects (VCRL syndrome) 23. Clinical severity ranges from severe prenatal lethality to mild presentations, even with identical mutations in siblings, indicating significant phenotypic heterogeneity 2. Functional studies demonstrate that pathogenic variants reduce protein levels or disrupt enzymatic activity 3. Affected pregnancies can be prevented through maternal supplementation with amidated NAD precursors (nicotinamide or nicotinamide mononucleotide) in homozygous mothers, while any B3 vitamer suffices for heterozygous mothers 1. A consistent NAD metabolome signature aids clinical diagnosis, and decreased plasmatic NAD levels should trigger screening for NADSYN1 variants even in patients with isolated organ involvement rather than the complete VCRL spectrum 21. Genetic variants in NADSYN1 are also associated with vitamin D metabolism and influenced Parkinson's disease clinical features in population studies 45, though these associations require further clarification.

Sources cited
1
NADSYN1 catalyzes the final step of NAD de novo synthesis; biallelic variants cause congenital NAD deficiency disorder with variable phenotypes; maternal NAD precursor supplementation prevents adverse outcomes
PMID: 38357931
2
NADSYN1 mutations cause VCRL syndrome; clinical presentation is heterogeneous; decreased plasma NAD levels warrant screening even for single organ involvement
PMID: 36951206
3
NADSYN1 encodes the final enzyme in NAD de novo synthesis; biallelic mutations cause congenital organ defects; pathogenic variants reduce protein levels or disrupt enzymatic activity
PMID: 34681008
4
NADSYN1 identified as a biomarker in B-cell acute lymphoblastic leukemia relapse with positive correlation to naive B cells
PMID: 36439178
5
NADSYN1/DHCR7 locus variants associated with clinical motor features in Parkinson's disease patients
PMID: 32938288
6
NADSYN1/DHCR7 associated with serum vitamin D levels in genome-wide association studies
PMID: 30316967
7
NADSYN1/DHCR7 variants significantly associated with lower plasma 25-hydroxyvitamin D levels in Chinese populations
PMID: 21972121
8
NADSYN1 biallelic variants cause cardiac and vertebral anomalies overlapping VATER/VACTERL association
PMID: 35491967
Disease Associationsβ“˜21
vertebral, cardiac, renal, and limb defects syndrome 3Open Targets
0.71Strong
congenital vertebral-cardiac-renal anomalies syndromeOpen Targets
0.63Moderate
Ulbright-Hodes syndromeOpen Targets
0.60Moderate
neurodegenerative diseaseOpen Targets
0.50Moderate
vitamin D deficiencyOpen Targets
0.37Weak
vitamin deficiency disorderOpen Targets
0.37Weak
Neurodevelopmental delayOpen Targets
0.34Weak
systemic lupus erythematosusOpen Targets
0.26Weak
multiple sclerosisOpen Targets
0.24Weak
genetic disorderOpen Targets
0.19Weak
type 1 diabetes nephropathyOpen Targets
0.12Weak
paralytic strabismusOpen Targets
0.12Weak
vertebral, cardiac, renal, and limb defects syndrome 1Open Targets
0.11Weak
Romano-Ward syndromeOpen Targets
0.06Suggestive
hypertrophic cardiomyopathyOpen Targets
0.06Suggestive
Rare familial disorder with hypertrophic cardiomyopathyOpen Targets
0.06Suggestive
Familial short QT syndromeOpen Targets
0.05Suggestive
catecholaminergic polymorphic ventricular tachycardiaOpen Targets
0.05Suggestive
Arrhythmogenic right ventricular dysplasiaOpen Targets
0.05Suggestive
Brugada syndromeOpen Targets
0.05Suggestive
Vertebral, cardiac, renal, and limb defects syndrome 3UniProt
Pathogenic Variants13
NM_018161.5(NADSYN1):c.524G>A (p.Cys175Tyr)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3
β˜…β˜…β˜†β˜†2025β†’ Residue 175
NM_018161.5(NADSYN1):c.1717G>A (p.Ala573Thr)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3|Congenital NAD deficiency disorder|not provided|Neurodevelopmental delay|NADSYN1-related disorder
β˜…β˜…β˜†β˜†2023β†’ Residue 573
NM_018161.5(NADSYN1):c.1459C>T (p.Arg487Ter)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3
β˜…β˜…β˜†β˜†2023β†’ Residue 487
NM_018161.5(NADSYN1):c.86-2A>CPathogenic
not provided
β˜…β˜†β˜†β˜†2025
NM_018161.5(NADSYN1):c.862C>T (p.Arg288Ter)Pathogenic
not provided
β˜…β˜†β˜†β˜†2025β†’ Residue 288
NM_018161.5(NADSYN1):c.1036C>T (p.Arg346Ter)Likely pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3
β˜…β˜†β˜†β˜†2025β†’ Residue 346
NM_018161.5(NADSYN1):c.85+1G>CPathogenic
NADSYN1-related disorder|not provided
β˜…β˜†β˜†β˜†2024
NM_018161.5(NADSYN1):c.1088C>T (p.Ala363Val)Likely pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3
β˜…β˜†β˜†β˜†2023β†’ Residue 363
NM_018161.5(NADSYN1):c.145T>C (p.Cys49Arg)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3|Congenital NAD deficiency disorder
β˜…β˜†β˜†β˜†2023β†’ Residue 49
NM_018161.5(NADSYN1):c.1744C>T (p.Gln582Ter)Likely pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3
β˜…β˜†β˜†β˜†β†’ Residue 582
NM_018161.5(NADSYN1):c.1839C>G (p.Tyr613Ter)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3|Congenital NAD deficiency disorder
β˜†β˜†β˜†β˜†2020β†’ Residue 613
NM_018161.5(NADSYN1):c.735T>A (p.Cys245Ter)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3|Congenital NAD deficiency disorder
β˜†β˜†β˜†β˜†2020β†’ Residue 245
NM_018161.5(NADSYN1):c.1819del (p.Val607fs)Pathogenic
Vertebral, cardiac, renal, and limb defects syndrome 3|Congenital NAD deficiency disorder
β˜†β˜†β˜†β˜†2020β†’ Residue 607
View on ClinVar β†—
Related Genes
CYP2R1Protein interaction96%SIRT1Protein interaction95%SIRT7Protein interaction95%H3-7Protein interaction95%BST1Protein interaction93%CD38Protein interaction93%
Tissue Expression6 tissues
Bone Marrow
100%
Lung
60%
Liver
59%
Ovary
51%
Heart
22%
Brain
9%
Gene Interaction Network
Click a node to explore
NADSYN1CYP2R1SIRT1SIRT7H3-7BST1CD38
PROTEIN STRUCTURE
Preparing viewer…
PDB6OFB Β· 2.84 Γ… Β· X-ray
View on RCSB β†—
Constraintβ“˜
LOEUFβ“˜
1.01LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.84 [0.70–1.01]
RankingsWhere NADSYN1 stands among ~20K protein-coding genes
  • #8,704of 20,598
    Most Researched51
  • #2,613of 5,498
    Most Pathogenic Variants13
  • #9,830of 17,882
    Most Constrained (LOEUF)1.01
Genes detectedNADSYN1
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
Integrating RNA-seq and scRNA-seq to explore the biological significance of NAD + metabolism-related genes in the initial diagnosis and relapse of childhood B-cell acute lymphoblastic leukemia.
PMID: 36439178
Front Immunol Β· 2022
1.00
2
PMID: 37499065
0.90
3
A metabolic signature for NADSYN1-dependent congenital NAD deficiency disorder.
PMID: 38357931
J Clin Invest Β· 2024
0.80
4
Genetic variants of vitamin D metabolism-related
PMID: 32938288
Int J Neurosci Β· 2022
0.70
5
Clinical heterogeneity of NADSYN1-associated VCRL syndrome.
PMID: 36951206
Clin Genet Β· 2023
0.60