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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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SLC29A3
solute carrier family 29 member 3
Chromosome 10 Β· 10q22.1
NCBI Gene: 55315Ensembl: ENSG00000198246.10HGNC: HGNC:23096UniProt: A0A2R8YDR8
54PubMed Papers
21Diseases
0Drugs
46Pathogenic Variants
FUNCTIONAL ROLE
Transporter
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
neurotransmitter transmembrane transporter activitynucleoside transmembrane transporter activityprotein bindingmonoamine transmembrane transporter activityH syndromeneurodegenerative diseasedysosteosclerosisDisorder of amino acid and other organic acid metabolism
✦AI Summary

SLC29A3 encodes equilibrative nucleoside transporter 3 (ENT3), a uniporter that facilitates nucleoside transport across lysosomal and mitochondrial membranes 123. The transporter functions as a non-electrogenic, Na+-independent system with pH-dependent activity enhanced under acidic conditions, reflecting its localization in acidic intracellular compartments 123. ENT3 transports various nucleosides (adenosine, guanosine, uridine, thymidine, cytidine, inosine), deoxynucleosides, nucleobases, and monoamine neurotransmitters, facilitating salvage synthesis of nucleic acids 1243. Loss-of-function mutations in SLC29A3 cause lysosomal nucleoside storage, leading to histiocytosis through TLR7/8-mediated stress responses that drive phagocyte proliferation and accumulation in multiple organs 5. These mutations are associated with H syndrome and related disorders including dysosteosclerosis, Faisalabad histiocytosis, and pigmented hypertrichosis with insulin-dependent diabetes 678. The clinical spectrum includes cutaneous hyperpigmentation, hypertrichosis, skeletal abnormalities, diabetes, and multisystemic involvement 910. ENT3 dysfunction also impacts cancer progression and chemotherapy efficacy, making it a potential therapeutic target 11.

Sources cited
1
ENT3 functions as uniporter mediating facilitative nucleoside transport across lysosomal and mitochondrial membranes
PMID: 15701636
2
ENT3 is non-electrogenic, Na+-independent, and transports nucleosides and monoamine neurotransmitters
PMID: 19164483
3
Transport is pH-dependent, enhanced under acidic conditions, and facilitates nucleoside salvage synthesis
PMID: 28729424
4
ENT3 transports nucleosides and deoxynucleosides
PMID: 20595384
5
SLC29A3 mutations cause lysosomal nucleoside storage and histiocytosis through TLR7/8-mediated phagocyte proliferation
PMID: 37462944
6
SLC29A3 mutations cause H syndrome and related disorders
PMID: 38965556
7
SLC29A3 mutations cause H syndrome, dysosteosclerosis, Faisalabad histiocytosis
PMID: 31464584
8
SLC29A3 mutations cause H syndrome affecting skin and vital organs
PMID: 27316388
9
H syndrome includes cutaneous hyperpigmentation, hypertrichosis, and multisystemic involvement
PMID: 39381726
10
SLC29A3 mutations cause dysosteosclerosis with skeletal abnormalities
PMID: 36402365
11
ENT3 impacts cancer progression and chemotherapy efficacy
PMID: 38104646
Disease Associationsβ“˜21
H syndromeOpen Targets
0.84Strong
neurodegenerative diseaseOpen Targets
0.44Moderate
dysosteosclerosisOpen Targets
0.38Weak
Disorder of amino acid and other organic acid metabolismOpen Targets
0.37Weak
generalized dystoniaOpen Targets
0.35Weak
acanthosis nigricansOpen Targets
0.33Weak
alcohol drinkingOpen Targets
0.33Weak
systemic lupus erythematosusOpen Targets
0.31Weak
genetic disorderOpen Targets
0.20Weak
ovarian dysfunctionOpen Targets
0.12Weak
digestive system neoplasmOpen Targets
0.09Suggestive
Varicose veinsOpen Targets
0.09Suggestive
isolated agammaglobulinemiaOpen Targets
0.06Suggestive
Familial hemophagocytic lymphohistiocytosisOpen Targets
0.06Suggestive
activated PI3K-delta syndromeOpen Targets
0.06Suggestive
MODYOpen Targets
0.05Suggestive
Adult-onset autosomal recessive sideroblastic anemiaOpen Targets
0.05Suggestive
Hemolytic anemia due to red cell pyruvate kinase deficiencyOpen Targets
0.05Suggestive
Chronic mucocutaneous candidosisOpen Targets
0.05Suggestive
X-linked immunodeficiency with magnesium defect, Epstein-Barr virus infection and neoplasiaOpen Targets
0.05Suggestive
Histiocytosis-lymphadenopathy plus syndromeUniProt
Pathogenic Variants46
NM_018344.6(SLC29A3):c.1309G>A (p.Gly437Arg)Pathogenic
H syndrome|not provided|Pigmentary skin disorders
β˜…β˜…β˜†β˜†2026β†’ Residue 437
NM_018344.6(SLC29A3):c.1279G>A (p.Gly427Ser)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2026β†’ Residue 427
NM_018344.6(SLC29A3):c.1087C>T (p.Arg363Trp)Pathogenic
H syndrome|not provided|SLC29A3-related disorder
β˜…β˜…β˜†β˜†2025β†’ Residue 363
NM_018344.6(SLC29A3):c.1088G>A (p.Arg363Gln)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 363
NM_018344.6(SLC29A3):c.1330G>T (p.Glu444Ter)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 444
NM_018344.6(SLC29A3):c.400C>T (p.Arg134Cys)Pathogenic
H syndrome
β˜…β˜…β˜†β˜†2025β†’ Residue 134
NM_018344.6(SLC29A3):c.479G>A (p.Trp160Ter)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 160
NM_018344.6(SLC29A3):c.971C>T (p.Pro324Leu)Pathogenic
H syndrome
β˜…β˜…β˜†β˜†2025β†’ Residue 324
NM_018344.6(SLC29A3):c.1228C>T (p.Gln410Ter)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2025β†’ Residue 410
NM_018344.6(SLC29A3):c.300+1G>CPathogenic
not provided|H syndrome
β˜…β˜…β˜†β˜†2025
NM_018344.6(SLC29A3):c.300+1G>APathogenic
H syndrome
β˜…β˜…β˜†β˜†2024
NM_018344.6(SLC29A3):c.1045del (p.Leu349fs)Pathogenic
H syndrome|not provided
β˜…β˜…β˜†β˜†2024β†’ Residue 349
NM_018344.6(SLC29A3):c.122del (p.Pro41fs)Pathogenic
H syndrome
β˜…β˜…β˜†β˜†2021β†’ Residue 41
NM_018344.6(SLC29A3):c.201dup (p.Trp68fs)Pathogenic
H syndrome
β˜…β˜†β˜†β˜†2025β†’ Residue 68
NM_018344.6(SLC29A3):c.611-1G>TLikely pathogenic
H syndrome|Thyroid cancer, nonmedullary, 1
β˜…β˜†β˜†β˜†2025
NM_018344.6(SLC29A3):c.347T>G (p.Met116Arg)Likely pathogenic
H syndrome|Clear cell carcinoma of kidney
β˜…β˜†β˜†β˜†2025β†’ Residue 116
NM_018344.6(SLC29A3):c.610+1G>ALikely pathogenic
H syndrome
β˜…β˜†β˜†β˜†2025
NM_018344.6(SLC29A3):c.67_70del (p.Leu24fs)Pathogenic
H syndrome
β˜…β˜†β˜†β˜†2025β†’ Residue 24
NM_018344.6(SLC29A3):c.383+1G>ALikely pathogenic
SLC29A3-related disorder|H syndrome
β˜…β˜†β˜†β˜†2025
NM_018344.6(SLC29A3):c.273_277dup (p.Asp93fs)Pathogenic
H syndrome
β˜…β˜†β˜†β˜†2024β†’ Residue 93
View on ClinVar β†—
Related Genes
CD63Protein interaction70%SLC29A2Protein interaction61%SLC28A2Protein interaction61%SLC28A3Protein interaction58%SLC29A1Protein interaction57%SLC28A1Protein interaction57%
Tissue Expression6 tissues
Ovary
100%
Liver
84%
Lung
38%
Heart
27%
Brain
25%
Bone Marrow
23%
Gene Interaction Network
Click a node to explore
SLC29A3CD63SLC29A2SLC28A2SLC28A3SLC29A1SLC28A1
PROTEIN STRUCTURE
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AlphaFoldAI-predicted Β· UniProt Q9BZD2
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
0.93LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.64 [0.44–0.93]
RankingsWhere SLC29A3 stands among ~20K protein-coding genes
  • #8,373of 20,598
    Most Researched54
  • #1,409of 5,498
    Most Pathogenic Variants46
  • #8,636of 17,882
    Most Constrained (LOEUF)0.93
Genes detectedSLC29A3
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
TLR7/8 stress response drives histiocytosis in SLC29A3 disorders.
PMID: 37462944
J Exp Med Β· 2023
1.00
2
A novel start-loss mutation of the SLC29A3 gene in a consanguineous family with H syndrome: clinical characteristics, in silico analysis and literature review.
PMID: 38965556
BMC Med Genomics Β· 2024
0.90
3
Equilibrative nucleotide transporter ENT3 (SLC29A3): A unique transporter for inherited disorders and cancers.
PMID: 38104646
Exp Cell Res Β· 2024
0.80
4
A novel homozygous frame-shift mutation in the SLC29A3 gene: a new case report and review of literature.
PMID: 31464584
BMC Med Genet Β· 2019
0.70
5
Compound heterozygous SLC29A3 mutation causes H syndrome in a Moroccan patient: A case report.
PMID: 27316388
Curr Res Transl Med Β· 2016
0.60