HomeAboutRankingsData Sources
© 2026 GeneE
🧬
GeneE
10 sources retrieved · Most recent: April 2026 · Index updated 14 days ago
ⓘGeneE is for informational purposes only. It is not a substitute for professional medical advice, diagnosis, or treatment.
USP36
ubiquitin specific peptidase 36
Chromosome 17 · 17q25.3
NCBI Gene: 57602Ensembl: ENSG00000055483.20HGNC: HGNC:20062UniProt: A0A075B784
112PubMed Papers
20Diseases
0Drugs
0Pathogenic Variants
FUNCTIONAL ROLE
Protease
DATA QUALITY
✓ Experimental GO Evidence✓ Swiss-Prot Reviewed
regulation of rRNA processinghistone H2B deubiquitinase activityK48-linked deubiquitinase activitynucleolusneurodegenerative diseaseatrial fibrillationliver cancerSjogren syndrome
✦AI Summary

USP36 is a nucleolar deubiquitinase essential for ribosomal RNA processing and nucleolar organization 123. As a K48-linked deubiquitinase, USP36 stabilizes critical ribosome biogenesis factors including DHX33, NPM1, and FBL through deubiquitination 123. Beyond its canonical nucleolar functions, USP36 regulates transcription by deubiquitinating histone H2B at differentiation-associated gene promoters like CDKN1A 4. Notably, USP36 specifically stabilizes nucleolar MYC through interaction with FBXW7gamma, counteracting SCF(FBW7)-mediated ubiquitination 5. Additionally, USP36 functions as a SUMO ligase promoting EXOSC10 sumoylation critical for rRNA processing 6. Clinically, USP36 is significantly upregulated in multiple cancers. In breast cancer, USP36 stabilizes estrogen receptor-α, promoting tamoxifen resistance 7. In colorectal cancer, USP36 inhibits p53 signaling by stabilizing RBM28 8 and blocks apoptosis through deubiquitinating survivin and cIAP1 9. In glioblastoma, USP36 stabilizes ALKBH5, enhancing tumorigenesis and reducing temozolomide sensitivity 10. USP36 also promotes solid tumor resistance to ribosome inhibitors through JNK-dependent Snail1 stabilization 11. Elevated USP36 correlates with poor prognosis in hepatocellular carcinoma and associates with increased immune checkpoint expression 12. Outside oncology, USP36-mediated PARP1 stabilization contributes to doxorubicin-induced cardiomyopathy 13.

Sources cited
1
Beyond its canonical nucleolar functions, USP36 regulates transcription by deubiquitinating histone H2B at differentiation-associated gene promoters like CDKN1A .
PMID: 29274341
2
Notably, USP36 specifically stabilizes nucleolar MYC through interaction with FBXW7gamma, counteracting SCF(FBW7)-mediated ubiquitination .
PMID: 25775507
3
Additionally, USP36 functions as a SUMO ligase promoting EXOSC10 sumoylation critical for rRNA processing .
PMID: 36912080
4
In breast cancer, USP36 stabilizes estrogen receptor-α, promoting tamoxifen resistance .
PMID: 39215346
5
In colorectal cancer, USP36 inhibits p53 signaling by stabilizing RBM28 and blocks apoptosis through deubiquitinating survivin and cIAP1 .
PMID: 39343961
6
In colorectal cancer, USP36 inhibits p53 signaling by stabilizing RBM28 and blocks apoptosis through deubiquitinating survivin and cIAP1 .
PMID: 38876304
7
In glioblastoma, USP36 stabilizes ALKBH5, enhancing tumorigenesis and reducing temozolomide sensitivity .
PMID: 36239338
8
USP36 also promotes solid tumor resistance to ribosome inhibitors through JNK-dependent Snail1 stabilization .
PMID: 37833415
9
Elevated USP36 correlates with poor prognosis in hepatocellular carcinoma and associates with increased immune checkpoint expression .
PMID: 35748266
10
Outside oncology, USP36-mediated PARP1 stabilization contributes to doxorubicin-induced cardiomyopathy .
PMID: 38307305
Disease Associationsⓘ20
neurodegenerative diseaseOpen Targets
0.35Weak
atrial fibrillationOpen Targets
0.27Weak
liver cancerOpen Targets
0.27Weak
Sjogren syndromeOpen Targets
0.26Weak
Myocardial IschemiaOpen Targets
0.25Weak
type 2 diabetes mellitusOpen Targets
0.23Weak
hypertensionOpen Targets
0.21Weak
heart failureOpen Targets
0.21Weak
coronary artery diseaseOpen Targets
0.17Weak
metabolic diseaseOpen Targets
0.16Weak
cardiovascular diseaseOpen Targets
0.13Weak
diabetes mellitusOpen Targets
0.09Suggestive
colorectal carcinomaOpen Targets
0.09Suggestive
breast cancerOpen Targets
0.08Suggestive
MODYOpen Targets
0.08Suggestive
gastric cancerOpen Targets
0.08Suggestive
esophageal squamous cell carcinomaOpen Targets
0.08Suggestive
ovarian cancerOpen Targets
0.07Suggestive
maturity-onset diabetes of the young type 3Open Targets
0.06Suggestive
diabetic nephropathyOpen Targets
0.06Suggestive
Pathogenic Variants
No pathogenic variants reported on ClinVar for this gene.
View on ClinVar ↗
Related Genes
DHX33Protein interaction85%ZUP1Protein interaction80%MYCProtein interaction74%USP42Shared pathway33%USP17L15Shared pathway30%USP17L22Shared pathway30%
Tissue Expression6 tissues
Bone Marrow
100%
Ovary
74%
Lung
53%
Liver
40%
Heart
29%
Brain
24%
Gene Interaction Network
Click a node to explore
USP36DHX33ZUP1MYCUSP42USP17L15USP17L22
PROTEIN STRUCTURE
Preparing viewer…
PDB8BS9 · 1.90 Å · X-ray
View on RCSB ↗
Constraintⓘ
LOEUFⓘ
0.65LoF Tolerant
pLIⓘ
0.00Tolerant
Observed/Expected LoF0.52 [0.42–0.65]
RankingsWhere USP36 stands among ~20K protein-coding genes
  • #4,255of 20,598
    Most Researched112 · top quartile
  • #4,636of 17,882
    Most Constrained (LOEUF)0.65
Genes detectedUSP36
Sources retrieved10 papers
Response time—
📄 Sources
10▼
1
USP36 promotes tumorigenesis and tamoxifen resistance in breast cancer by deubiquitinating and stabilizing ERα.
PMID: 39215346
J Exp Clin Cancer Res · 2024
1.00
2
USP36 promotes colorectal cancer progression through inhibition of p53 signaling pathway via stabilizing RBM28.
PMID: 39343961
Oncogene · 2024
0.90
3
USP36 stabilizes nucleolar Snail1 to promote ribosome biogenesis and cancer cell survival upon ribotoxic stress.
PMID: 37833415
Nat Commun · 2023
0.80
4
USP36 promotes tumorigenesis and drug sensitivity of glioblastoma by deubiquitinating and stabilizing ALKBH5.
PMID: 36239338
Neuro Oncol · 2023
0.70
5
USP36 inhibits apoptosis by deubiquitinating cIAP1 and survivin in colorectal cancer cells.
PMID: 38876304
J Biol Chem · 2024
0.60