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GeneE
10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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ATXN7
ataxin 7
Chromosome 3 Β· 3p14.1
NCBI Gene: 6314Ensembl: ENSG00000163635.21HGNC: HGNC:10560UniProt: O15265
120PubMed Papers
21Diseases
0Drugs
3Pathogenic Variants
FUNCTIONAL ROLE
Highly ConstrainedTranscription Factor
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
microtubule cytoskeleton organizationcytosolmicrotubule cytoskeletonregulation of transcription by RNA polymerase IIspinocerebellar ataxia 7type 2 diabetes mellitusneurodegenerative diseaseschizophrenia
✦AI Summary

ATXN7 (ataxin 7) is a component of the SAGA transcription coactivator-HAT complex that mediates interactions with the CRX transcription factor for gene activation 1. The protein plays dual roles in nuclear and cytoplasmic functions: it regulates transcription by RNA polymerase II and stabilizes the microtubule cytoskeleton 2, likely through tethering the deubiquitination module within the SAGA complex 3. ATXN7's primary clinical significance relates to spinocerebellar ataxia 7 (SCA7), a neurological repeat expansion disorder caused by CAG repeat expansions in the ATXN7 gene 4. CAG repeat mosaicism in SCA7 increases over time and correlates with disease manifestation, with higher expansion levels in symptomatic versus asymptomatic carriers 4. SCA7 patients demonstrate cerebellar cognitive-affective syndrome in 67% of cases, correlating with ataxia severity and plasma neurofilament light chain levels 5. Beyond ataxia, emerging evidence suggests ATXN7 has broader oncogenic significance; ATXN7 mutations cooperate with RAS in thyroid tumorigenesis 6, and Rad51C-ATXN7 fusion genes appear in colorectal cancers 7. Additionally, ATXN7 genetic variants predict hepatocellular carcinoma prognosis 8.

Sources cited
1
ATXN7 acts as a component of the SAGA transcription coactivator complex and mediates CRX-dependent gene activation
PMID: 15932940
2
ATXN7 is necessary for microtubule cytoskeleton stabilization
PMID: 22100762
3
ATXN7 is probably involved in tethering the deubiquitination module within the SAGA complex
PMID: 24493646
4
CAG repeat mosaicism in SCA7 increases over time and correlates with disease manifestation in symptomatic carriers
PMID: 38626762
5
SCA7 patients have 67% prevalence of cerebellar cognitive-affective syndrome correlating with ataxia severity and neurofilament light chain levels
PMID: 40834346
6
ATXN7 mutations cooperate with oncogenic RAS to induce thyroid cell proliferation and tumorigenesis
PMID: 28584132
7
Rad51C-ATXN7 fusion genes are expressed in colorectal tumors and may impair DNA repair pathways
PMID: 27296891
8
ATXN7 gene variants and low expression are associated with hepatocellular carcinoma prognosis
PMID: 27855399
Disease Associationsβ“˜21
spinocerebellar ataxia 7Open Targets
0.63Moderate
type 2 diabetes mellitusOpen Targets
0.53Moderate
neurodegenerative diseaseOpen Targets
0.48Moderate
schizophreniaOpen Targets
0.47Moderate
diabetes mellitusOpen Targets
0.46Moderate
cerebellar ataxiaOpen Targets
0.37Weak
breast carcinomaOpen Targets
0.36Weak
diabetic neuropathyOpen Targets
0.31Weak
diabetic retinopathyOpen Targets
0.30Weak
lens diseaseOpen Targets
0.27Weak
Tip-toe gaitOpen Targets
0.26Weak
cataractOpen Targets
0.21Weak
ovarian neoplasmOpen Targets
0.20Weak
genetic disorderOpen Targets
0.19Weak
Retinal dystrophyOpen Targets
0.17Weak
bipolar disorderOpen Targets
0.16Weak
Tourette syndromeOpen Targets
0.16Weak
attention deficit hyperactivity disorderOpen Targets
0.15Weak
autism spectrum disorderOpen Targets
0.14Weak
obsessive-compulsive disorderOpen Targets
0.14Weak
Spinocerebellar ataxia 7UniProt
Pathogenic Variants3
NM_001377405.1(ATXN7):c.89AGC[233] (p.Gln39_Pro40insGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGlnGln)Pathogenic
Spinocerebellar ataxia 7
β˜…β˜†β˜†β˜†2019β†’ Residue 39
NM_001377405.1(ATXN7):c.1141C>T (p.Arg381Ter)Likely pathogenic
not provided
β˜†β˜†β˜†β˜†2025β†’ Residue 381
NM_001377405.1(ATXN7):c.2119C>A (p.Arg707Ser)Likely pathogenic
Tip-toe gait
β˜†β˜†β˜†β˜†β†’ Residue 707
View on ClinVar β†—
Related Genes
TRRAPProtein interaction100%TADA2AProtein interaction100%TAF9Protein interaction100%SGF29Protein interaction100%TAF10Protein interaction100%TADA3Protein interaction100%
Tissue Expression6 tissues
Lung
100%
Ovary
82%
Liver
70%
Brain
46%
Bone Marrow
9%
Heart
3%
Gene Interaction Network
Click a node to explore
ATXN7TRRAPTADA2ATAF9SGF29TAF10TADA3
PROTEIN STRUCTURE
Preparing viewer…
PDB7KTR Β· 2.93 Γ… Β· EM
View on RCSB β†—
Constraintβ“˜
LOEUFβ“˜
0.26Highly Constrained
pLIβ“˜
1.00Intolerant
Observed/Expected LoF0.15 [0.09–0.26]
RankingsWhere ATXN7 stands among ~20K protein-coding genes
  • #3,907of 20,598
    Most Researched120 Β· top quartile
  • #3,973of 5,498
    Most Pathogenic Variants3
  • #816of 17,882
    Most Constrained (LOEUF)0.26 Β· top 5%
Genes detectedATXN7
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
Attention-deficit/hyperactive disorder updates.
PMID: 36211978
Front Mol Neurosci Β· 2022
1.00
2
ATXN7 Gene Variants and Expression Predict Post-Operative Clinical Outcomes in Hepatitis B Virus-Related Hepatocellular Carcinoma.
PMID: 27855399
Cell Physiol Biochem Β· 2016
0.90
3
Whole genome sequencing for the diagnosis of neurological repeat expansion disorders in the UK: a retrospective diagnostic accuracy and prospective clinical validation study.
PMID: 35182509
Lancet Neurol Β· 2022
0.80
4
CAG repeat mosaicism is gene specific in spinocerebellar ataxias.
PMID: 38626762
Am J Hum Genet Β· 2024
0.70
5
Transposon mutagenesis identifies chromatin modifiers cooperating with
PMID: 28584132
Proc Natl Acad Sci U S A Β· 2017
0.60