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10 sources retrieved Β· Most recent: April 2026 Β· Index updated 14 days ago
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SLC7A14
solute carrier family 7 member 14
Chromosome 3 Β· 3q26.2
NCBI Gene: 57709Ensembl: ENSG00000013293.6HGNC: HGNC:29326UniProt: Q8TBB6
19PubMed Papers
21Diseases
0Drugs
4Pathogenic Variants
FUNCTIONAL ROLE
Transporter
CLINICAL
OMIM Disease Gene
DATA QUALITY
βœ“ Experimental GO Evidenceβœ“ Swiss-Prot Reviewed
protein bindingamino acid transmembrane transporter activitygamma-aminobutyric acid transmembrane transporter activitygamma-aminobutyric acid importretinitis pigmentosaRetinal dystrophyAlzheimer diseaseAbruptio Placentae
✦AI Summary

SLC7A14 is a cationic amino acid transporter that mediates lysosomal uptake of gamma-aminobutyrate (GABA) and other cationic amino acids 1. The protein is highly expressed in lysosomes of retinal photoreceptors and cochlear inner hair cells, where it functions in nutrient sensing and cellular homeostasis 1. SLC7A14 may act as a GABA sensor regulating mTORC2-dependent insulin signaling and gluconeogenesis, though the complete transport mechanism requires further elucidation. Mutations in SLC7A14 cause autosomal recessive retinitis pigmentosa (arRP), accounting for approximately 2% of arRP cases 2. SLC7A14 is specifically expressed in the mammalian photoreceptor layer, and its expression increases during postnatal retinal development 2. Loss-of-function mutations impair protein trafficking and increase basal autophagy, leading to progressive photoreceptor and inner hair cell degeneration 1. This results in syndromic sensory disease presenting as presynaptic auditory neuropathy and retinitis pigmentosa 1. Additionally, SLC7A14 variants have been identified through genome-wide association studies as candidate genes affecting insulin processing and secretion, with potential relevance to type 2 diabetes risk 3. The phenotypic variability of SLC7A14 mutations, including presentations as both retinitis pigmentosa and Leber congenital amaurosis, demonstrates its critical role in retinal development and visual function 4.

Sources cited
1
SLC7A14 mediates lysosomal uptake of cationic amino acids; expressed in cochlear and retinal lysosomes; mutations cause auditory neuropathy and retinitis pigmentosa through autophagy-lysosomal dysfunction
PMID: 35394837
2
SLC7A14 mutations account for 2% of autosomal recessive RP cases; specifically expressed in photoreceptor layer with increased expression during postnatal retinal development; essential for retinal development and visual function
PMID: 24670872
3
SLC7A14 is a candidate gene identified through GWAS for proinsulin levels and insulin processing, with potential relevance to type 2 diabetes risk mechanisms
PMID: 36693378
4
SLC7A14 mutations cause phenotypic variability including both retinitis pigmentosa and Leber congenital amaurosis presentations
PMID: 30924391
5
SLC7A14 identified as disease-causing gene in Chinese families with retinitis pigmentosa through targeted panel and whole exome sequencing
PMID: 31960602
Disease Associationsβ“˜21
retinitis pigmentosaOpen Targets
0.76Strong
Retinal dystrophyOpen Targets
0.38Weak
Alzheimer diseaseOpen Targets
0.37Weak
Abruptio PlacentaeOpen Targets
0.31Weak
Parkinson diseaseOpen Targets
0.31Weak
lysosomal storage diseaseOpen Targets
0.31Weak
multiple sclerosisOpen Targets
0.31Weak
neurodegenerative diseaseOpen Targets
0.31Weak
COVID-19Open Targets
0.30Weak
ovarian neoplasmOpen Targets
0.30Weak
Varicose veinsOpen Targets
0.26Weak
cervical carcinomaOpen Targets
0.25Weak
lymphatic system diseaseOpen Targets
0.20Weak
vein disorderOpen Targets
0.19Weak
optic atrophyOpen Targets
0.11Weak
deafnessOpen Targets
0.08Suggestive
hearing loss, autosomal recessiveOpen Targets
0.08Suggestive
autosomal dominant nonsyndromic hearing lossOpen Targets
0.07Suggestive
Usher syndromeOpen Targets
0.07Suggestive
Usher syndrome type 1COpen Targets
0.06Suggestive
Retinitis pigmentosa 68UniProt
Pathogenic Variants4
NM_020949.3(SLC7A14):c.1778A>G (p.Gln593Arg)Likely pathogenic
Retinal dystrophy
β˜…β˜†β˜†β˜†2023β†’ Residue 593
NM_020949.3(SLC7A14):c.1682C>T (p.Thr561Met)Likely pathogenic
Retinal dystrophy
β˜…β˜†β˜†β˜†2023β†’ Residue 561
NM_020949.3(SLC7A14):c.2122T>G (p.Phe708Val)Pathogenic
Retinitis pigmentosa 68
β˜†β˜†β˜†β˜†2014β†’ Residue 708
NM_020949.3(SLC7A14):c.395C>T (p.Ala132Val)Pathogenic
Retinitis pigmentosa 68
β˜†β˜†β˜†β˜†2014β†’ Residue 132
View on ClinVar β†—
Related Genes
FRRS1LProtein interaction77%SLC7A4Shared pathway50%SLC6A12Shared pathway33%SLC38A4Shared pathway33%SLC43A2Shared pathway29%SLC16A10Shared pathway29%
Tissue Expression6 tissues
Brain
100%
Ovary
3%
Liver
1%
Lung
0%
Bone Marrow
0%
Heart
0%
Gene Interaction Network
Click a node to explore
SLC7A14FRRS1LSLC7A4SLC6A12SLC38A4SLC43A2SLC16A10
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted Β· UniProt Q8TBB6
View on AlphaFold β†—
Constraintβ“˜
LOEUFβ“˜
0.78LoF Tolerant
pLIβ“˜
0.00Tolerant
Observed/Expected LoF0.59 [0.45–0.78]
RankingsWhere SLC7A14 stands among ~20K protein-coding genes
  • #14,545of 20,598
    Most Researched19
  • #3,863of 5,498
    Most Pathogenic Variants4
  • #6,371of 17,882
    Most Constrained (LOEUF)0.78
Genes detectedSLC7A14
Sources retrieved10 papers
Response timeβ€”
πŸ“„ Sources
10β–Ό
1
PMID: 20301590
1.00
2
Application of targeted panel sequencing and whole exome sequencing for 76 Chinese families with retinitis pigmentosa.
PMID: 31960602
Mol Genet Genomic Med Β· 2020
0.90
3
Loci for insulin processing and secretion provide insight into type 2 diabetes risk.
PMID: 36693378
Am J Hum Genet Β· 2023
0.80
4
SLC7A14 linked to autosomal recessive retinitis pigmentosa.
PMID: 24670872
Nat Commun Β· 2014
0.70
5
Phenotypic variability of SLC7A14 mutations in patients with inherited retinal dystrophy.
PMID: 30924391
Ophthalmic Genet Β· 2019
0.60