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10 sources retrieved · Most recent: April 2026 · Index updated 14 days ago
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LRP12
LDL receptor related protein 12
Chromosome 8 · 8q22.3
NCBI Gene: 29967Ensembl: ENSG00000147650.12HGNC: HGNC:31708UniProt: Q59H02
33PubMed Papers
22Diseases
0Drugs
1Pathogenic Variants
FUNCTIONAL ROLE
Highly ConstrainedReceptor
CLINICAL
OMIM Disease Gene
DATA QUALITY
✓ Experimental GO Evidence✓ Swiss-Prot Reviewed
protein bindingneuron migrationneuron projection developmentplasma membraneoculopharyngodistal myopathyoculopharyngodistal myopathy 1amyotrophic lateral sclerosis 28hypertension
✦AI Summary

LRP12 (LDL receptor-related protein 12) is a probable receptor involved in lipophilic molecule internalization and signal transduction, with emerging roles in neuromuscular and neoplastic disease. The protein localizes to clathrin-coated pits and the plasma membrane, consistent with endocytic function 1. LRP12 mutations cause oculopharyngodistal myopathy type 1 (OPDM1), characterized by progressive ocular, facial, pharyngeal, and distal limb weakness with pathological rimmed vacuoles and intranuclear inclusions 2. Disease-causing variants involve CGG repeat expansions in the 5'-untranslated region 3. Importantly, repeat length determines phenotypic switching: individuals with 61-100 repeats develop amyotrophic lateral sclerosis (ALS) with phosphorylated TDP-43 pathology in motor neurons, while those with 100-200 repeats present as OPDM 4. Both phenotypes feature RNA foci formation, though the underlying toxic mechanisms involve repeat length-dependent differences in RNA and protein gain-of-function 4. Beyond neuromuscular disease, LRP12 functions as a regulator of gastric cancer progression through AKT/mTOR signaling activation and M2 macrophage-mediated immunosuppression, suggesting a tumor-promoting role distinct from its classic receptor functions 5. LRP12 thus represents a multifunctional protein with context-dependent roles in neurodegenerative disease, myopathy, and cancer biology.

Sources cited
1
LRP12 is associated with autosomal dominant distal myopathy and localizes to clathrin-coated pits and plasma membrane
PMID: 33458580
2
CGG repeat expansions in LRP12 5'-UTR cause OPDM1 with progressive ocular, facial, pharyngeal and distal weakness featuring rimmed vacuoles and intranuclear inclusions
PMID: 35942670
3
Noncoding CGG repeat expansions in LRP12 are identified as causative mutations for oculopharyngodistal myopathy
PMID: 31332380
4
CGG repeat expansion in LRP12 causes ALS with 61-100 repeats and OPDM with 100-200 repeats, demonstrating repeat length-dependent phenotypic switching with TDP-43 pathology in ALS
PMID: 37339631
5
LRP12 promotes gastric cancer progression through AKT/mTOR signaling activation and M2 macrophage-mediated immunosuppression
PMID: 41276539
Disease Associationsⓘ22
oculopharyngodistal myopathyOpen Targets
0.47Moderate
oculopharyngodistal myopathy 1Open Targets
0.45Moderate
amyotrophic lateral sclerosis 28Open Targets
0.43Moderate
hypertensionOpen Targets
0.41Moderate
type 2 diabetes mellitusOpen Targets
0.40Moderate
amyotrophic lateral sclerosisOpen Targets
0.38Weak
respiratory tract infectious disorderOpen Targets
0.31Weak
atrial fibrillationOpen Targets
0.30Weak
alcohol drinkingOpen Targets
0.29Weak
Increased blood pressureOpen Targets
0.25Weak
atrial flutterOpen Targets
0.23Weak
cardiovascular diseaseOpen Targets
0.22Weak
benign chondrogenic neoplasmOpen Targets
0.22Weak
placental retentionOpen Targets
0.22Weak
cerebrovascular disorderOpen Targets
0.21Weak
Abnormal abdomen morphologyOpen Targets
0.21Weak
open-angle glaucomaOpen Targets
0.20Weak
cardiac arrhythmiaOpen Targets
0.20Weak
genetic disorderOpen Targets
0.19Weak
response to xenobiotic stimulusOpen Targets
0.19Weak
Amyotrophic lateral sclerosis 28UniProt
Oculopharyngodistal myopathy 1UniProt
Pathogenic Variants1
NM_013437.5:c.-102CGG[(90_?)]Pathogenic
Oculopharyngodistal myopathy 1|Amyotrophic lateral sclerosis 28
☆☆☆☆2023
View on ClinVar ↗
Related Genes
NOTCH2NLCProtein interaction63%DNERShared pathway29%CEP85LShared pathway25%GPRIN3Shared pathway25%ENTHD1Shared pathway25%GPRIN1Shared pathway25%
Tissue Expression6 tissues
Heart
100%
Brain
80%
Ovary
23%
Bone Marrow
20%
Lung
19%
Liver
6%
Gene Interaction Network
Click a node to explore
LRP12NOTCH2NLCDNERCEP85LGPRIN3ENTHD1GPRIN1
PROTEIN STRUCTURE
Preparing viewer…
AlphaFoldAI-predicted · UniProt Q59H02
View on AlphaFold ↗
Constraintⓘ
LOEUFⓘ
0.29Highly Constrained
pLIⓘ
1.00Intolerant
Observed/Expected LoF0.19 [0.12–0.29]
RankingsWhere LRP12 stands among ~20K protein-coding genes
  • #11,364of 20,598
    Most Researched33
  • #5,236of 5,498
    Most Pathogenic Variants1
  • #1,073of 17,882
    Most Constrained (LOEUF)0.29 · top 10%
Genes detectedLRP12
Sources retrieved10 papers
Response time—
📄 Sources
10▼
1
Panorama of the distal myopathies.
PMID: 33458580
Acta Myol · 2020
1.00
2
A 20-year Clinical and Genetic Neuromuscular Cohort Analysis in Lebanon: An International Effort.
PMID: 34602496
J Neuromuscul Dis · 2022
0.90
3
Oculopharyngodistal myopathy.
PMID: 35942670
Curr Opin Neurol · 2022
0.80
4
Noncoding CGG repeat expansions in neuronal intranuclear inclusion disease, oculopharyngodistal myopathy and an overlapping disease.
PMID: 31332380
Nat Genet · 2019
0.70
5
CGG repeat expansion in LRP12 in amyotrophic lateral sclerosis.
PMID: 37339631
Am J Hum Genet · 2023
0.60